- short premaxilla / MGI
- short maxilla / MGI
- abnormal frontal bone morphology / MGI
- hypertension / MGI
- abnormal heart morphology / MGI
- heart right ventricle hypertrophy / MGI
- abnormal cranium morphology / MGI
- abnormal mammary gland development / MGI
- mammary gland hyperplasia / MGI
- abnormal branching of the mammary ductal tree / MGI
- abnormal blood vessel morphology / MGI
- increased mammary adenocarcinoma incidence / MGI
- neoplasm / MGI
- heart left ventricle hypertrophy / MGI
- increased systemic arterial blood pressure / MGI
- short zygomatic bone / MGI
- abnormal facial morphology / MGI
- abnormal lip morphology / MGI
- renal fibrosis / MGI
- renal/urinary system phenotype / MGI
- cardiovascular system phenotype / MGI
- respiratory system phenotype / MGI
- abnormal circulating protein level / MGI
- increased systemic arterial diastolic blood pressure / MGI
- increased systemic arterial systolic blood pressure / MGI
- enlarged heart atrium / MGI
- increased heart ventricle size / MGI
- abnormal aorta tunica media morphology / MGI
- abnormal vibrissa follicle morphology / MGI
- enlarged aortic valve / MGI
- decreased urine creatinine level / MGI
- depressed nasal bridge / MGI
- short nasal bridge / MGI
- choanal stenosis / MGI
B6.129(Cg)-Hrastm2Xbr/Cnbc
Status | Available to order |
EMMA ID | EM:05942 |
International strain name | B6.129(Cg)-Hrastm2Xbr/Cnbc |
Alternative name | Hras1 |
Strain type | Targeted Mutant Strains : Conditional mutation |
Allele/Transgene symbol | Hrastm2Xbr |
Gene/Transgene symbol | Hras |
Information from provider
Provider | Mariano Barbacid |
Provider affiliation | Molecular Oncology, Centro Nacional de Investigaciones Oncologicas |
Genetic information | In ES cells containing Hras1tm1Xbr, in which an IRES-beta-geo cassette was integrated into the 3'-UTR of the Hras gene, a floxed hygro STOP cassette was inserted upstream of coding exon 1. In addition, a G to T substitution was created at the second base of codon 12 of exon 1. This results in an amino acid substitution of valine for glycine at position 12. Upon cre-mediated recombination, removal of the hygro STOP cassette leads to the expression of the HrasG12V mutation and the IRES-beta-geo cassette so that the lacZ reporter is expressed in those cells that express the mutated HrasG12V gene. |
Phenotypic information | Before cre-mediated recombination there is no phenotype associated to this allele. After germ-line cre-mediated excision of the floxed STOP hygro cassette, expression of the HrasG12V mutant leads to multiple abnormalities, mostly related to craniofacial, cardiovascular and mammary gland development and tumorigenesis. This is a mouse model of human Costello syndrome. |
Breeding history | Chimeras were crossed with CD1 females for germ line transmission analysis. Heterozygous offspring were crossed among themselves to generate homozygous mutants. Heterozygous animals were backcrossed to C57BL/6J for more than 10 generations. After cre-mediated recombination homozygous mice HrasG12V/G12V are viable and fertile. |
References |
|
Homozygous fertile | yes |
Homozygous viable | yes |
Homozygous matings required | no |
Immunocompromised | no |
Information from EMMA
Archiving centre | CNB-CSIC, Centro Nacional de Biotecnologia, Madrid, Spain |
Animals used for archiving | heterozygous C57BL/6J |
Disease and phenotype information
MGI allele-associated human disease models
Orphanet associated rare diseases, based on orthologous gene matching
- Phakomatosis pigmentokeratotica / Orphanet_2874
- Linear nevus sebaceus syndrome / Orphanet_2612
- Woolly hair nevus / Orphanet_79414
- Differentiated thyroid carcinoma / Orphanet_146
- Costello syndrome / Orphanet_3071
MGI phenotypes (allele matching)
MGI phenotypes (gene matching)
- short premaxilla / MGI
- short maxilla / MGI
- abnormal frontal bone morphology / MGI
- hypertension / MGI
- abnormal heart morphology / MGI
- heart right ventricle hypertrophy / MGI
- abnormal cranium morphology / MGI
- abnormal mammary gland development / MGI
- mammary gland hyperplasia / MGI
- abnormal branching of the mammary ductal tree / MGI
- abnormal blood vessel morphology / MGI
- increased mammary adenocarcinoma incidence / MGI
- neoplasm / MGI
- no abnormal phenotype detected / MGI
- heart left ventricle hypertrophy / MGI
- increased systemic arterial blood pressure / MGI
- no phenotypic analysis / MGI
- short zygomatic bone / MGI
- nervous system phenotype / MGI
- abnormal facial morphology / MGI
- abnormal lip morphology / MGI
- renal fibrosis / MGI
- decreased incidence of tumors by chemical induction / MGI
- renal/urinary system phenotype / MGI
- cardiovascular system phenotype / MGI
- respiratory system phenotype / MGI
- abnormal circulating protein level / MGI
- increased systemic arterial diastolic blood pressure / MGI
- increased systemic arterial systolic blood pressure / MGI
- enlarged heart atrium / MGI
- increased heart ventricle size / MGI
- abnormal aorta tunica media morphology / MGI
- abnormal vibrissa follicle morphology / MGI
- enlarged aortic valve / MGI
- decreased urine creatinine level / MGI
- chylous ascites / MGI
- depressed nasal bridge / MGI
- short nasal bridge / MGI
- choanal stenosis / MGI
Literature references
- A mouse model for Costello syndrome reveals an Ang II-mediated hypertensive condition.;Schuhmacher Alberto J, Guerra Carmen, Sauzeau Vincent, Cañamero Marta, Bustelo Xosé R, Barbacid Mariano, ;2008;The Journal of clinical investigation;118;2169-79; 18483625
- Germline expression of H-Ras(G12V) causes neurological deficits associated to Costello syndrome.;Viosca J, Schuhmacher A J, Guerra C, Barco A, ;2009;Genes, brain, and behavior;8;60-71; 18823404
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