- abnormal digit morphology / IMPC
- abnormal autopod morphology / IMPC
- abnormal zygomatic bone morphology / IMPC
- abnormal pelvic girdle bone morphology / IMPC
- abnormal brain morphology / IMPC
- abnormal nail morphology / IMPC
- increased lean body mass / IMPC
- abnormal vertebrae morphology / IMPC
- abnormal vertebral arch morphology / IMPC
- increased grip strength / IMPC
- decreased prepulse inhibition / IMPC
- decreased total body fat amount / IMPC
- abnormal cranium morphology / IMPC
PDT/Pas
Status | Available to order |
EMMA ID | EM:01165 |
International strain name | PDT/Pas |
Alternative name | polydactyly |
Strain type | Induced Mutant Strains : Chemically-induced |
Allele/Transgene symbol | Twist1Pas |
Gene/Transgene symbol | Twist1 |
Information from provider
Provider | Jean-Louis Guénet |
Provider affiliation | Institut Pasteur |
Genetic information | This ENU induced mutation was found to be allelic through complementation analysis with a known allele at the Twist1 locus. No sequence alteration was found in the coding region of the gene. A decrease in transcript was noted by in situ hybridization. |
Phenotypic information | Homozygous mutant embyros have neural tube defects and die around E11. Heterozygous mutants are viable and exhibit features of human Saethre-Chotzen syndrome, including hindlimb polydactyly and craniofacial defects. |
Breeding history | Bred by crossing heterozygous and wild-type mice. |
References |
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Information from EMMA
Archiving centre | Institut de Transgenose, INTRAGENE, Orléans, France |
Disease and phenotype information
MGI allele-associated human disease models
Orphanet associated rare diseases, based on orthologous gene matching
- Saethre-Chotzen syndrome / Orphanet_794
- Isolated scaphocephaly / Orphanet_35093
- Isolated brachycephaly / Orphanet_35099
- Isolated plagiocephaly / Orphanet_35098
IMPC phenotypes (gene matching)
MGI phenotypes (gene matching)
- premature cranial suture closure / MGI
- cleft palate / MGI
- abnormal rib morphology / MGI
- short limbs / MGI
- abnormal forelimb morphology / MGI
- polydactyly / MGI
- abnormal muscle development / MGI
- exencephaly / MGI
- open neural tube / MGI
- decreased body size / MGI
- abnormal gait / MGI
- internal hemorrhage / MGI
- abnormal limb morphology / MGI
- abnormal limb bone morphology / MGI
- premature endochondral bone ossification / MGI
- nervous system phenotype / MGI
- enlarged interparietal bone / MGI
- temporal bone hypoplasia / MGI
- abnormal clavicle morphology / MGI
- craniofacial phenotype / MGI
- skeleton phenotype / MGI
- abnormal bone ossification / MGI
- abnormal osteoblast differentiation / MGI
- short temporal bone squamous part / MGI
- neonatal lethality, complete penetrance / MGI
- embryonic lethality, complete penetrance / MGI
- prenatal lethality, incomplete penetrance / MGI
- premature coronal suture closure / MGI
- premature lambdoid suture closure / MGI
Literature references
- A new mouse limb mutation identifies a Twist allele that requires interacting loci on chromosome 4 for its phenotypic expression.;Blanc Isabelle, Bach Antoine, Lallemand Yvan, Perrin-Schmitt Fabienne, Guénet Jean-Louis, Robert Benoît, ;2003;Mammalian genome : official journal of the International Mammalian Genome Society;14;797-804; 14724733
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